Longitudinal analysis of a dominantly inherited Alzheimer disease mutation carrier protected from dementia – Nature.com

Longitudinal analysis of a dominantly inherited Alzheimer disease mutation carrier protected from dementia – Nature.com

Source: Nature.com

Thank you for visiting nature.com. You are using a browser version with limited support for CSS. To obtain

the best experience, we recommend you use a more up to date browser (or turn off compatibility mode in

Internet Explorer). In the meantime, to ensure continued support, we are displaying the site without styles

and JavaScript.

Nature Medicine

(2025)Cite this article

We conducted an in-depth longitudinal study on an individual carrying the presenilin 2 p.Asn141Ile mutation, traditionally associated with dominantly inherited Alzheimer’s disease (AD), who has remarkably remained asymptomatic past the expected age of clinical onset. This study combines genetic, neuroimaging and biomarker analyses to explore the underpinnings of this resilience. Unlike typical progression in dominantly inherited AD, tau pathology in this case was confined to the occipital region without evidence of spread, potentially explaining the preservation of cognitive functions. Genetic analysis revealed several variants that, although not previously associated with protection against AD, suggest new avenues for understanding disease resistance. Notably, environmental factors such as significant heat exposure and a unique proteomic profile rich in heat shock proteins might indicate adaptive mechanisms contributing to the observed phenotype. This case underscores the complexity of Alzheimer’s pathology and suggests that blocking tau deposition could be a promising target for therapeutic intervention. The study highlights the need for further research to identify and validate the mechanisms that could inhibit or localize tau pathology as a strategy to mitigate or delay the onset of Alzheimer’s dementia.

This is a preview of subscription content, access via your institution

Access Nature and 54 other Nature Portfolio journals

Get Nature+, our best-value online-access subscription

Receive 12 print issues and online access

Prices may be subject to local taxes which are calculated during checkout

Data and study samples (for example, CSF, plasma) supporting the findings of this study are available on request and will follow the policies of the DIAN (https://dian.wustl.edu), which comply with the guidelines established by the Collaboration for Alzheimer’s Prevention. De-identified whole-genome sequencing data will be made available through NIAGADS as part of the DIAN data-sharing process.

The codes used in this study, including those applied for segregation analysis, are openly accessible at the following repository: https://github.com/NeuroGenomicsAndInformatics/escapee.

Bateman, R. J. et al. Clinical and biomarker changes in dominantly inherited Alzheimer’s disease. N. Engl. J. Med. 367, 795–804 (2012).

Article 

PubMed 

PubMed Central 

CAS 

Google Scholar 

Tang, M. et al. Neurological manifestations of autosomal dominant familial Alzheimer’s disease: a comparison of the published literature with the Dominantly Inherited Alzheimer Network observational study (DIAN-OBS). Lancet Neurol. 15, 1317–1325 (2016).

Article 

PubMed 

PubMed Central 

Google Scholar 

Ryman, D. C. et al. Symptom onset in autosomal dominant Alzheimer disease: a systematic review and meta-analysis. Neurology 83, 253–260 (2014).

McDade, E. et al. Longitudinal cognitive and biomarker changes in dominantly inherited Alzheimer disease. Neurology 91, e1295–e1306 (2018).

Article 

PubMed 

PubMed Central 

Google Scholar 

Rabinovici, G. D. Dominantly inherited Alzheimer’s disease: a compass for drug development. Nat. Med. https://doi.org/10.1038/s41591-021-01434-2 (2021).

Salloway, S. et al. A trial of gantenerumab or solanezumab in dominantly inherited Alzheimer’s disease. Nat. Med. https://doi.org/10.1038/s41591-021-01369-8 (2021).

Morris, J. C. et al. Developing an international network for Alzheimer research: the Dominantly Inherited Alzheimer Network. Clin. Investig. (Lond.) 2, 975–984 (2012).

Article 

PubMed 

CAS 

Google Scholar 

Arboleda-Velasquez, J. F. et al. Resistance to autosomal dominant Alzheimer’s disease in an APOE3 Christchurch homozygote: a case report. Nat. Med. 25, 1680–1683 (2019).

Article 

PubMed 

PubMed Central 

CAS 

Google Scholar 

Kriebs, A. Genetic protection from early-onset familial Alzheimer’s disease. Nat. Aging 3, 635 (2023).

Article 

PubMed 

Google Scholar 

Lopera, F. et al. Resilience to autosomal dominant Alzheimer’s disease in a Reelin-COLBOS heterozygous man. Nat. Med. 29, 1243–1252 (2023).

Article 

PubMed 

PubMed Central 

CAS 

Google Scholar 

Quiroz, Y. T. et al. APOE3 Christchurch he

Read more: Click here

Leave a Comment